PURPOSE: Herein, we report a rare case of recurrent hematocornea due to a non-pigmented adenoma of the ciliary body and its successful management with repeated deep anterior lamellar keratoplasty (DALK). OBSERVATIONS: A 27-year-old man presented with significant visual acuity loss in his only functional eye due to hematocornea. Initial management involved visco-DALK, which restored visual acuity to 0.8. After 6 months, recurrent hematocornea prompted the removal of the underlying neoplasm through a scleral approach, which was histologically confirmed as a non-pigmented adenoma of the ciliary body. A repeat DALK was performed, followed by phacoemulsification with intraocular lens implantation for subsequent cataract development. Postoperative recovery was uneventful, and visual acuity stabilized at 0.8. CONCLUSIONS AND IMPORTANCE: This case highlights the feasibility and efficacy of visco-DALK in managing hematocornea while preserving endothelial integrity. The approach facilitated subsequent interventions, including neoplasm excision, repeat DALK, and cataract surgery, with favorable visual outcomes.

Department of Ophthalmic Oncology and Radiology Moscow Helmholtz Research Institute of Eye Diseases Moscow Russian Federation

Department of Ophthalmology Astghik Medical Center Yerevan Armenia

Department of Ophthalmology Crystal Vision Bahrаin Specialist Hospital Manama Bahrain

Faculty of Medicine The Charles University Prague Czech Republic

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